Proptosis Due to Isolated Intra-Orbital Meningocele- A Case Report
,
Abstract
Congenital orbital wall defects are very rare bone abnormalities that can cause protrusion of intracranial contents into the orbit. The protrusion of the meninges, which encompasses cerebrospinal fluid (CSF), result in a condition known as the orbital meningocele, a rare cause of pulsatile proptosis. Here, we present a 4-year-old female with left eye proptosis referred to our clinic. On magnetic resonance imaging (MRI), a cystic structure was present. The patient underwent surgery for cyst removal. CSF leakage was noted during surgery. Computed tomography (CT) scan revealed a bony defect in the sphenoid greater wing and the resulting meningocele. Craniotomy surgery was performed to close and fill the defect.
[1] Rozzi R, Behringer J, Obajuluwa A, Wilczynski M. Spontaneous Unilateral Intrasphenoidal Meningocele. J
Radiol Case Rep. 2020 Aug 31;14(8):1-7. doi: 10.3941/jrcr.v14i8.3761. PMID: 33088417; PMCID: PMC7535999.
[2] van Rumund A, Verrips A, Verhagen WIM. Pulsatile Proptosis due to Intraorbital Meningocele. Front Neurol. 2017 Jun 19;8:290. doi: 10.3389/fneur.2017.00290. PMID: 28674516; PMCID: PMC5474481.
[3] Topilow NJ, Tran AQ, Koo EB, Alabiad CR. Etiologies of Proptosis: A review. Intern Med Rev (Wash D C). 2020 Mar;6(3):10.18103/imr.v6i3.852. DOI: 10.18103/imr.v6i3.852. PMID: 32382689; PMCID: PMC7204542.
[4]Benharbit, M., Rifi L, L., El Khamlichi, A., & Mohcine, Z. (2004). La méningo-encéphalocèle orbitaire. A propos
de 2 cas [Orbital meningoencephalocele: two case studies]. Journal francais d'ophtalmologie, 27(6 Pt 1), 613–616. https://doi.org/10.1016/s0181- 5512(04)96186-4
[5] Haug RH, Van Sickels JE, Jenkins WS. Demographics and treatment options for orbital roof fractures. Oral Surg Oral Med Oral Pathol Oral Radiol Endod. 2002 Mar;93(3):238-46. DOI: 10.1067/moe.2002.120975. PMID: 11925530.
[6]Umerani MS, Burhan H, Sharif S, Islam TU, Ghaziani MH. Orbital Meningoencephalocele and Pulsatile Proptosis: A Rare Entity. Cureus. 2018 Jan 15;10(1):e2064. DOI: 10.7759/cureus.2064. PMID: 29552427; PMCID: PMC5854304.
[7]Badilla, J., & Dolman, P. J. (2007). Cerebrospinal fluid leaks complicating orbital or oculoplastic surgery.
Archives of ophthalmology (Chicago, Ill. : 1960), 125(12), 1631–1634. https://doi.org/10.1001/archopht.125.12.1631
[8]Heo JJ, Chong JH, Han JJ, Jung S, Kook MS, Oh HK, Park HJ. Reconstruction of the orbital wall using superior orbital rim osteotomy in a patient with a superior orbital wall fracture. Maxillofac Plast Reconstr Surg. 2018 Dec 4;40(1):42. doi: 10.1186/s40902-018-0181-1. PMID: 30581811; PMCID: PMC6277397.
[9]Mbaye, M., Thiam, A. B., Cissue, M. A., Faye, M., Ndiaye, S., Thioub, M., Ndoye, N., Code Ba, M., & Badiane, S. B. (2020). Orbital meningocele in two case studies. Surgical neurology international, 11, 119. https://doi.org/10.25259/SNI_148_2020
[10] Consul, B. N., & Kulshrestha, O. P. (1965). Orbital meningocele. The British journal of ophthalmology, 49(7), 374–376. https://doi.org/10.1136/bjo.49.7.374
[11] Ha AY, Mangham W, Frommer SA, Choi D, Klinge P, Taylor HO, Oyelese AA, Sullivan SR. Interdisciplinary Management of Minimally Displaced Orbital Roof Fractures: Delayed Pulsatile Exophthalmos and Orbital Encephalocele. Craniomaxillofac Trauma Reconstr. 2017 Mar;10(1):11-15. doi: 10.1055/s-0036-1584395. Epub 2016 Sep 15. PMID: 28210402; PMCID: PMC5305309.
Radiol Case Rep. 2020 Aug 31;14(8):1-7. doi: 10.3941/jrcr.v14i8.3761. PMID: 33088417; PMCID: PMC7535999.
[2] van Rumund A, Verrips A, Verhagen WIM. Pulsatile Proptosis due to Intraorbital Meningocele. Front Neurol. 2017 Jun 19;8:290. doi: 10.3389/fneur.2017.00290. PMID: 28674516; PMCID: PMC5474481.
[3] Topilow NJ, Tran AQ, Koo EB, Alabiad CR. Etiologies of Proptosis: A review. Intern Med Rev (Wash D C). 2020 Mar;6(3):10.18103/imr.v6i3.852. DOI: 10.18103/imr.v6i3.852. PMID: 32382689; PMCID: PMC7204542.
[4]Benharbit, M., Rifi L, L., El Khamlichi, A., & Mohcine, Z. (2004). La méningo-encéphalocèle orbitaire. A propos
de 2 cas [Orbital meningoencephalocele: two case studies]. Journal francais d'ophtalmologie, 27(6 Pt 1), 613–616. https://doi.org/10.1016/s0181- 5512(04)96186-4
[5] Haug RH, Van Sickels JE, Jenkins WS. Demographics and treatment options for orbital roof fractures. Oral Surg Oral Med Oral Pathol Oral Radiol Endod. 2002 Mar;93(3):238-46. DOI: 10.1067/moe.2002.120975. PMID: 11925530.
[6]Umerani MS, Burhan H, Sharif S, Islam TU, Ghaziani MH. Orbital Meningoencephalocele and Pulsatile Proptosis: A Rare Entity. Cureus. 2018 Jan 15;10(1):e2064. DOI: 10.7759/cureus.2064. PMID: 29552427; PMCID: PMC5854304.
[7]Badilla, J., & Dolman, P. J. (2007). Cerebrospinal fluid leaks complicating orbital or oculoplastic surgery.
Archives of ophthalmology (Chicago, Ill. : 1960), 125(12), 1631–1634. https://doi.org/10.1001/archopht.125.12.1631
[8]Heo JJ, Chong JH, Han JJ, Jung S, Kook MS, Oh HK, Park HJ. Reconstruction of the orbital wall using superior orbital rim osteotomy in a patient with a superior orbital wall fracture. Maxillofac Plast Reconstr Surg. 2018 Dec 4;40(1):42. doi: 10.1186/s40902-018-0181-1. PMID: 30581811; PMCID: PMC6277397.
[9]Mbaye, M., Thiam, A. B., Cissue, M. A., Faye, M., Ndiaye, S., Thioub, M., Ndoye, N., Code Ba, M., & Badiane, S. B. (2020). Orbital meningocele in two case studies. Surgical neurology international, 11, 119. https://doi.org/10.25259/SNI_148_2020
[10] Consul, B. N., & Kulshrestha, O. P. (1965). Orbital meningocele. The British journal of ophthalmology, 49(7), 374–376. https://doi.org/10.1136/bjo.49.7.374
[11] Ha AY, Mangham W, Frommer SA, Choi D, Klinge P, Taylor HO, Oyelese AA, Sullivan SR. Interdisciplinary Management of Minimally Displaced Orbital Roof Fractures: Delayed Pulsatile Exophthalmos and Orbital Encephalocele. Craniomaxillofac Trauma Reconstr. 2017 Mar;10(1):11-15. doi: 10.1055/s-0036-1584395. Epub 2016 Sep 15. PMID: 28210402; PMCID: PMC5305309.
| Files | ||
| Issue | Vol 8 No 1 (2023): Janyary-February | |
| Section | Case Report(s) | |
| DOI | https://doi.org/10.18502/crcp.v8i1.13100 | |
| Keywords | ||
| Meningocele Orbital Child | ||
| Rights and permissions | |
|
This work is licensed under a Creative Commons Attribution-NonCommercial 4.0 International License. |
How to Cite
1.
Taher Rajabi M, Mohammadi A, Besharati S. Proptosis Due to Isolated Intra-Orbital Meningocele- A Case Report. CRCP. 2023;8(1):42-45.
